Dental appliance therapy in pantothenate kinase-associated neurodegeneration: Case report

Thomas Cooper, Leon Smith

Research output: Contribution to specialist publicationArticle

1 Citation (Scopus)

Abstract

Pantothenate kinase-associated neurodegeneration (PKAN) is a rare condition associated with severe protrusive lingual dystonia, a form of oromandibular dystonia. Dental appliance therapy has been described for oromandibular dystonia however there is a lack of literature regarding its application specifically to PKAN. In this report, the authors describe the use of an appliance in conjunction with botulinum toxin injections for the symptomatic treatment of this condition. A satisfactory outcome is achieved which suggests this technique may be of use to other clinicians.

Original languageEnglish
Pages56-58
Number of pages3
Volume39
No.1
Specialist publicationSpecial Care in Dentistry
DOIs
Publication statusPublished - 2019

Cite this

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title = "Dental appliance therapy in pantothenate kinase-associated neurodegeneration: Case report",
abstract = "Pantothenate kinase-associated neurodegeneration (PKAN) is a rare condition associated with severe protrusive lingual dystonia, a form of oromandibular dystonia. Dental appliance therapy has been described for oromandibular dystonia however there is a lack of literature regarding its application specifically to PKAN. In this report, the authors describe the use of an appliance in conjunction with botulinum toxin injections for the symptomatic treatment of this condition. A satisfactory outcome is achieved which suggests this technique may be of use to other clinicians.",
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Dental appliance therapy in pantothenate kinase-associated neurodegeneration : Case report. / Cooper, Thomas; Smith, Leon.

In: Special Care in Dentistry, Vol. 39, No. 1, 2019, p. 56-58.

Research output: Contribution to specialist publicationArticle

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AB - Pantothenate kinase-associated neurodegeneration (PKAN) is a rare condition associated with severe protrusive lingual dystonia, a form of oromandibular dystonia. Dental appliance therapy has been described for oromandibular dystonia however there is a lack of literature regarding its application specifically to PKAN. In this report, the authors describe the use of an appliance in conjunction with botulinum toxin injections for the symptomatic treatment of this condition. A satisfactory outcome is achieved which suggests this technique may be of use to other clinicians.

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